Strain Specific Resistance to Murine Scrapie Associated with a Naturally Occurring Human Prion Protein Polymorphism at Residue 171
2011

Study of Prion Disease Resistance in Mice with Human Prion Protein Variation

Sample size: 43 publication 10 minutes Evidence: moderate

Author Information

Author(s): James F. Striebel, Brent Race, Kimberly D. Meade-White, Rachel LaCasse, Bruce Chesebro

Primary Institution: Laboratory of Persistent Viral Diseases and Rocky Mountain Laboratories, National Institute of Allergy and Infectious Diseases, Hamilton, Montana, United States of America

Hypothesis

Does the N171S polymorphism in human prion protein affect susceptibility to prion diseases in a mouse model?

Conclusion

Transgenic mice expressing the N171S variant of prion protein showed resistance to certain scrapie strains, indicating strain-specific interactions.

Supporting Evidence

  • Transgenic mice expressing the N171S variant were resistant to RML and 79A scrapie strains.
  • Resistance was not observed with ME7 and 22L scrapie strains.
  • Clinical disease in transgenic mice occurred only after 439 days post-inoculation with RML and 79A strains.

Takeaway

Scientists created special mice to see if a human gene change makes them resistant to a brain disease. Some mice were resistant to certain types of the disease, but not all.

Methodology

Transgenic mice expressing the N171S variant of prion protein were tested with four different strains of scrapie to assess susceptibility.

Limitations

The low incidence of the N171S polymorphism in humans limits the ability to study its effects directly in human populations.

Participant Demographics

Transgenic mice expressing the human prion protein variant.

Statistical Information

P-Value

p<0.001

Statistical Significance

p<0.001

Digital Object Identifier (DOI)

10.1371/journal.ppat.1002275

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