Association between celiac sprue and cryopyrin associated autoinflammatory disorders: a case report
2007

Celiac Disease and Cryopyrinopathy in a Child

Sample size: 1 publication Evidence: low

Author Information

Author(s): Shaker Marcus, Edwards Susan, Chionuma Henry, Shamansky Eric, Hoffman Hal M

Primary Institution: Dartmouth-Hitchcock Medical Center

Hypothesis

Is there an association between celiac disease and cryopyrin-associated autoinflammatory disorders?

Conclusion

The case suggests a possible association between celiac disease and cryopyrinopathy, although the co-occurrence may be coincidental.

Supporting Evidence

  • The child presented with recurrent fevers and gastrointestinal symptoms.
  • Genetic testing revealed a mutation associated with cryopyrinopathy.
  • A gluten-free diet improved gastrointestinal symptoms but not fevers or rashes.
  • This is the first report of a cryopyrinopathy in a patient with celiac disease.

Takeaway

A young child had both celiac disease and a rare condition called cryopyrinopathy, which usually causes fevers and rashes.

Methodology

The case involved clinical evaluation, laboratory tests, and genetic analysis.

Limitations

The findings are based on a single case, limiting generalizability.

Participant Demographics

A 2-year-old Caucasian girl with a family history of celiac disease.

Digital Object Identifier (DOI)

10.1186/1546-0096-5-12

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